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Anorectal malformation with didelphys uterus: Extremely rare anomaly and successful neoanal sphincter reconstruction with gracilis muscle flap

Archives of Plastic Surgery 2020년 47권 3호 p.272 ~ 276
Burusapat Chairat, Hongkarnjanakul Natthawoot, Wanichjaroen Nutthapong, Panitwong Sakchai, Sangkaewsuntisuk Jiraporn, Boonya-ussadorn Chinakrit,
소속 상세정보
 ( Burusapat Chairat ) - Phramongkutklao Hospital Department of Surgery
 ( Hongkarnjanakul Natthawoot ) - Phramongkutklao Hospital Department of Surgery
 ( Wanichjaroen Nutthapong ) - Phramongkutklao Hospital Department of Surgery
 ( Panitwong Sakchai ) - Phramongkutklao College of Medicine Phramongkutklao Hospital Department of Obstetrics and Gynecology
 ( Sangkaewsuntisuk Jiraporn ) - Phramongkutklao College of Medicine Phramongkutklao Hospital Department of Surgery
 ( Boonya-ussadorn Chinakrit ) - Phramongkutklao College of Medicine Phramongkutklao Hospital Department of Surgery

Abstract


Anorectal malformation or imperforate anus is a congenital anomaly of rectum and anus. Mullerian duct anomalies are abnormal development of uterus, cervix, and vagina. Imperforate anus with double uterus is extremely rare and cannot explain by normal embryologic development. Moreover, guideline in treatment is inconclusive. We report an extremely rare case of a young adult female who presented with recurrent pelvic inflammatory disease caused by rectovaginal fistula in congenital imperforate anus and didelphys uterus, and successfully neoanal reconstruction with gracilis muscle flap. Aims for treatment are closed rectovaginal fistula, and anal sphincter reconstruction. To our best knowledge, the imperforate anus with double uterus is extremely rare anomaly. Furthermore, successfully anal sphincter reconstruction with functional gracilis muscle in the imperforate anus with double uterus has never been reported in English literature.

키워드

Anorectal malformation; Didelphys uterus; Rectovaginal fistula; Gracilis muscle

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